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April 11, 2026JAMA Ophthalmology0 citations

Clinical and Genetic Spectrum of ACO2 -Linked Dominant Optic Atrophy

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CBCléis BeaulieuABAymane BouzidiVDValérie Desquiret-Dumas

Key Points

  • This research aims to explore the clinical and genetic diversity associated with ACO2-related dominant optic atrophy.
  • Conducted a case series of patients with ACO2-related DOA
  • Analyzed clinical presentations and retinal abnormalities
  • Investigated for large genomic rearrangements in patients lacking molecular diagnosis
  • Observed high clinical heterogeneity among ACO2-related DOA patients
  • Some patients exhibited retinal abnormalities
  • Identified an entire exon deletion in ACO2, highlighting the need for further genetic evaluations

Abstract

Results of this case series reveal the high clinical heterogeneity among patients with ACO2-related DOA and demonstrated that some of these patients can also exhibit retinal abnormalities. In addition, there was a deletion of an entire ACO2 exon, emphasizing the potential importance of searching for large genomic rearrangements in patients without a molecular diagnosis. These findings support further studies to explain clinical variability, as no genotype-phenotype correlation was encountered.

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Cite This Study

Beaulieu et al. (2026) studied this question.

synapsesocial.com/papers/69d9e5ec78050d08c1b761cfhttps://doi.org/10.1001/jamaophthalmol.2026.0634
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