PulseExploreJournal ClubDebatesTrendingResearchersJournals
Instagram
HomeExploreJournal ClubTrending
Synapse
⌘+K
Synapse
May 16, 2026Indian Pediatrics Case Reports0 citationsOpen Access

Du Pan Syndrome with Autoamputation of Digits in a Neonate: A Case Report

View Full Paper
STSonali TanpureALAtul LondheLDLaxmikant Deshmukh

Key Points

  • To report a case of Du Pan Syndrome with unique vascular complications in a neonate and examine the role of the GDF5 gene.
  • Clinical examination of a term male neonate with digit abnormalities.
  • Radiographs confirmed fibular aplasia and Doppler evaluation assessed arterial flow.
  • Whole-exome sequencing identified a homozygous mutation in the GDF5 gene.
  • The neonate presented with severe brachydactyly and absent arterial flow in the left great toe.
  • Autoamputation of both great toes occurred due to necrosis.
  • Follow-up revealed normal neurodevelopment yet persistent brachydactyly.

Abstract

Abstract Background: Du Pan Syndrome (DPS) (OMIM 228900) is a rare autosomal recessive skeletal dysplasia caused by variants in the GDF5 gene. It is distinguished by complex brachydactyly and fibular aplasia/hypoplasia, a type of acromesomelic dysplasia. Clinical Description: A term male neonate born out of third-degree consanguineous marriage, presented with abnormalities of the digits of the upper and lower limbs. Antenatal scans had detected soft tissue swelling around the second great toe. Examination revealed a length C(p.Leu441Pro) was discovered by whole-exome sequencing. The neonate was managed conservatively. Genetic counselling was provided to the parents. On follow-up, the infant had normal neurodevelopment with persistent brachydactyly. Conclusion: This case broadens the phenotypic spectrum of DPS by demonstrating a new vascular phenotype, suggesting the possible role of the GDF5 gene in angiogenesis.

Ask AI
Helpful
Bookmark
Share
View Full Paper

Cite This Study

Tanpure et al. (2026) studied this question.

synapsesocial.com/papers/6a080b38a487c87a6a40d6e5https://doi.org/10.4103/ipcares.ipcares_248_25
Ask AI
Helpful
Bookmark
Share
View Full Paper